Interactive Genomic Exploration · Motor Neuron Disease

The Genetics of ALS

An interactive journey through the human genome to understand why motor neurons die — and what role genes like C9orf72, SOD1 and TDP-43 play.

Discover
0
Familial cases (the rest, sporadic)
0
Genes associated with ALS
0
Genes curated in this atlas
0
Key cellular mechanisms
The story at a glance

From a gene to the motor neuron that shuts down

The entire journey of this page, summarized in steps.

Starting point
Genes (C9orf72 · SOD1 · TARDBP · FUS)
The molecular damage
Abnormal protein / toxic RNA
They accumulate
Aggregates (TDP-43)
The target cell
Motor neuron damage
The muscle
Muscle without signal
Outcome
Progressive weakness
The disease

What is ALS?

Before diving into the genetics, it helps to know the disease that these genes help explain.

Amyotrophic lateral sclerosis (ALS) is the most common motor neuron disease. The neurons that control voluntary movement —the upper motor neurons (in the brain) and the lower motor neurons (in the spinal cord and brainstem)— degenerate progressively. The muscle stops receiving signals, weakens and atrophies. Most cases share a single hallmark: aggregates of the TDP-43 protein.

~2/100,000
New cases per year (approximate incidence)
50–65 years
Typical age of onset (varies widely)
~10%
Familial forms (the rest, sporadic)
Motor neuron
Affects the neurons of voluntary movement
Origin

From Charcot to genetics

In 1869, the French neurologist Jean-Martin Charcot described and named the disease, linking the loss of strength to the degeneration of the motor pathways. For more than a century it was a purely clinical entity; the genetic era began in 1993 with the discovery of SOD1.

Symptoms

When the muscle loses its command

Symptoms depend on which motor neurons are affected first, and they combine as the disease progresses:

Upper motor neuron

Spasticity

Stiffness and spasticity, brisk reflexes and clumsy movements. It is the signature of the motor pathways descending from the brain.

Lower motor neuron

Weakness and atrophy

Weakness, muscle atrophy and fasciculations (small twitches visible under the skin) when the neuron that reaches the muscle is damaged.

Bulbar symptoms

Speech and swallowing

Difficulty speaking and swallowing when the brainstem motor neurons are affected. Sometimes this is the first sign of the disease.

Cognitive sphere

Overlap with FTD

Up to ~15% develop associated frontotemporal dementia (changes in behavior and language). ALS, by contrast, spares the senses and sphincter control.

Profiles

Not all ALS is the same

The majority

Sporadic

Around 90% of cases appear with no clear family history. Genetics still contributes risk, alongside aging and environmental factors.

~10%

Familial

Inheritance is usually dominant. The most common genes are C9orf72, SOD1, TARDBP and FUS.

A single spectrum

ALS-FTD overlap

ALS and frontotemporal dementia share genes (above all C9orf72) and pathology (TDP-43): they are two ends of a single continuum.

Over time

A progressive disease

ALS usually begins focally (in a hand, a leg or speech) and spreads to other regions of the body.

Focal onset

Weakness or clumsiness in a specific area: a hand, a foot or problems with speech/swallowing.

Spread

Weakness and atrophy propagate to adjacent regions and to the other side of the body.

Generalization

Several muscle groups are affected; dependence for daily activities increases.

Respiratory phase

Weakness reaches the respiratory muscles: ventilatory support becomes key.

Treatment

Modest but real, and increasingly targeted

There is no cure, but a multidisciplinary approach improves quality of life and survival, and genetics is opening specific therapies.

Drugs

Riluzole and edaravone

Riluzole (reduces excitotoxicity) and edaravone (an antioxidant) offer a modest benefit on progression. They do not stop the disease.

Support

Multidisciplinary team

Respiratory support (ventilation) and nutritional support, physical therapy, speech therapy and communication aids: the cornerstone of care.

Genetic medicine

Tofersen for SOD1

Tofersen, an antisense oligonucleotide (ASO), treats ALS caused by SOD1 mutations: the first gene-targeted therapy in this disease.

Educational content with a scientific basis (Charcot, 1869; SOD1, Rosen et al. 1993; C9orf72, DeJesus-Hernandez/Renton 2011; tofersen, Miller et al. 2022). It does not replace assessment by a healthcare professional.

Foundation

What is DNA?

DNA (deoxyribonucleic acid) is the molecule that stores the genetic instructions of every living being, distributed across some 3 billion base pairs.

Four bases — A, T, C and G — form the double helix. In ALS, many variants affect proteins that handle RNA or clear other proteins: when they fail, toxic aggregates form in the motor neurons.

A — Adenine
T — Thymine
C — Cytosine
G — Guanine
Interactive

Explore the genome

ALS genes are spread across the entire genome. Click on a chromosome to see its regions, the evidence and the genes involved.

Gene atlas

Gene catalog

Causal and risk genes for ALS. Search and filter by cellular mechanism; click a card to see its function and the studies.

Functional convergence

Cellular mechanisms

ALS genes converge on a few motor neuron processes. Hover over a node to identify the gene; click to see the details.

Interactive

From the repeat to the motor neuron

Two key pieces of ALS: the GGGGCC expansion in C9orf72 and the motor neuron → muscle circuit. Explore them.

The most common genetic cause

The G4C2 repeat in C9orf72

The C9orf72 gene contains a stretch where the GGGGCC hexanucleotide is repeated. Healthy people have few repeats; when it expands to hundreds or thousands, it generates toxic RNA and dipeptides and reduces the normal protein. Slide to see the effect.

8GGGGCC repeats
Normal

The motor circuit

From the upper motor neuron to the muscle

The command to move travels in two relays. In ALS both degenerate. Click on each step of the diagram.

A century and a half of science

Timeline of discoveries

From Charcot's description to the C9orf72 gene and the first approved antisense therapy.

Biology

Biological processes involved

How ALS genes damage the motor neurons that control voluntary movement.

What the data say

Is ALS inherited?

Most ALS cases are sporadic: around 90%. Only ~10% are familial, although both share the same mechanisms.

0%
Familial cases (inheritance, usually dominant)
0%
Of familial cases are due to C9orf72

C9orf72 is the most common genetic cause (familial and sporadic) and links ALS to frontotemporal dementia. SOD1, the first gene discovered, already has a targeted drug. Even in "sporadic" cases, genetics contributes a substantial part of the risk.

Estimated heritability of ALS risk~50%

Twin and SNP studies suggest that about half of the risk is genetic; the rest includes environmental and aging factors.

Conclusions

What do we know for certain?

The essentials about the genetics of amyotrophic lateral sclerosis:

The most important point: identifying the gene already changes treatment. SOD1 ALS has an approved antisense therapy (tofersen), and others are being investigated for C9orf72 and FUS. Genetics is, at last, opening targeted therapies.

Therapeutic avenues: where does each one stand?
Already in clinical use

Drugs and support

  • Riluzole and edaravone: modest benefit on progression
  • Tofersen (ASO): approved in 2023 for SOD1 ALS
  • Multidisciplinary respiratory and nutritional support
In clinical trials

Silencing specific genes

  • ASOs against C9orf72 to reduce the toxic RNA from the expansion
  • Gene therapies (including the one targeting FUS) in clinical development
  • Biomarkers such as neurofilaments to measure the effect
Preclinical research

Attacking the cause

  • Gene editing (CRISPR) to correct causal mutations
  • Targets on TDP-43 and the cryptic exons that appear when it fails
  • Anti-aggregation and proteostasis strategies
Myths

What ALS is NOT

ALS is a neurodegenerative disease. It is worth dispelling some misconceptions:

It is not contagious It is not a cancer or a tumor It does not affect the senses (sight, hearing) It usually does not affect sphincter control It is not caused by exertion or sport on their own

The so-called "Ice Bucket Challenge" (2014) was a viral awareness campaign that raised funds for ALS research; it is not a cause or a risk factor, but a public-awareness milestone.

The frontier

The latest and what's coming

Genetics is turning ALS into an increasingly targetable disease.

Recent advances

What is changing the field

Gene-targeted therapy

Tofersen and ASOs

Tofersen (approved in 2023) silences SOD1 RNA and has been shown to reduce neurofilaments. It is the proof of concept that treating the gene works, and it opens the door to ASOs for other genes.

The most common challenge

Therapies against C9orf72

Because C9orf72 is the most frequent genetic cause, ASOs that reduce the toxic RNA from the GGGGCC expansion are one of the great hopes; several are in clinical trials.

Measuring better

Biomarkers

Neurofilaments in blood and cerebrospinal fluid make it possible to estimate neuronal damage and the response to treatment, accelerating trials.

Future directions

Where research is heading

Precision

Genetic medicine

Sequencing each person to choose the therapy according to their gene: ALS is moving toward treatment personalized by mutation.

TDP-43

Correcting the common hallmark

Restoring TDP-43 function and blocking the cryptic exons (such as the one in UNC13A) could help most cases, not only the genetic ones.

Treating earlier

Early diagnosis

Detecting the disease —even before symptoms in known carriers— in order to intervene while there are still motor neurons left to protect.

Research is advancing quickly and some of these findings are preliminary: specific dates and figures may change as the trials mature.

Frequently asked questions

Common questions

The questions that come up most when learning about ALS.

Is ALS hereditary?
Mostly, no: around 90% of cases are sporadic, with no clear family history. Only ~10% are familial, usually with dominant inheritance (C9orf72, SOD1, TARDBP, FUS). Even so, genetics also contributes risk in sporadic cases.
Is this the one from the "Ice Bucket Challenge"?
Yes. The Ice Bucket Challenge (2014) was a viral campaign to raise awareness and funds for ALS research. It was public outreach: it is not a cause or a risk factor for the disease.
Does ALS affect the mind?
In most people, intelligence, memory and the senses are preserved. However, up to ~15% develop associated frontotemporal dementia, and many more show mild cognitive or behavioral changes. ALS and FTD share genes and pathology.
Is there a cure?
For now, no. Riluzole and edaravone offer a modest benefit, and multidisciplinary support improves quality of life. The new development is tofersen, a therapy targeting the SOD1 gene, which points the way for genetic treatments.
Is there a genetic test?
Yes. The main genes can be studied (above all C9orf72, SOD1, TARDBP and FUS). It is especially useful in familial cases and now also guides treatment (e.g., tofersen for SOD1). Always with genetic counseling.
Is ALS contagious?
No. ALS is not transmitted from person to person by any means. It is a neurodegenerative disease with a genetic and aging basis, not an infection.
Sources and glossary

Where this comes from

Milestones and scientific sources on which this page is based.

Foundational milestones
1869Charcot JM. Description of amyotrophic lateral sclerosis as a motor neuron disease (lectures at the Salpêtrière).
1993Rosen DR et al. Mutations in Cu/Zn superoxide dismutase gene are associated with familial ALS. Nature. The first gene (SOD1).
2008Neumann M et al. / Sreedharan J et al. TDP-43 as the protein of the aggregates and TARDBP as the causal gene.
The most common gene and the therapy
2011DeJesus-Hernandez M et al.; Renton AE et al. Expanded GGGGCC hexanucleotide repeat in C9ORF72 causes ALS and FTD. Neuron. The most common genetic cause.
2022Miller TM et al. Trial of antisense oligonucleotide tofersen for SOD1 ALS. N Engl J Med. The tofersen trial (ASO for SOD1).
Databases
DatabasesOMIM #105400, ALSoD and the Project MinE consortium.

A synthesizing educational page; it is not a primary clinical source. For medical decisions, consult professionals and the official resources of ALS associations.

Glossary

Key terms

Motor neuronThe neuron that commands voluntary movement.
There are two: the upper (in the brain) and the lower (in the spinal cord and brainstem), which connects to the muscle. In ALS both degenerate, and the muscle is left without signal.
TDP-43The protein whose aggregates are the hallmark of ALS.
It normally lives in the nucleus and regulates RNA. In nearly all ALS it moves to the cytoplasm and aggregates, leaving the neuron without control of its RNA (encoded by the TARDBP gene).
C9orf72The most common gene in ALS (and in ALS-FTD).
It contains a repeat of the GGGGCC hexanucleotide. When it expands to hundreds or thousands of copies, it produces toxic RNA and dipeptides: the most frequent genetic cause of ALS.
SOD1The first gene discovered; today with a targeted therapy.
It encodes an antioxidant enzyme. Its mutations cause the protein to aggregate (toxic gain of function). It is the target of the drug tofersen.
Sporadic vs. familialWithout or with a family history.
Sporadic (~90%): no evident family history. Familial (~10%): inherited, usually in a dominant manner. Both share mechanisms and pathology.
ALS-FTDThe overlap with frontotemporal dementia.
ALS and frontotemporal dementia share genes (above all C9orf72) and TDP-43 pathology. They are understood as two ends of a single disease continuum.
FasciculationsSmall visible muscle twitches.
They are involuntary twitches of small groups of fibers, visible under the skin. They reflect lower motor neuron damage and are a characteristic sign of ALS.
ASO (antisense oligonucleotide)A strand that silences a specific RNA.
A small nucleic-acid molecule that binds the RNA of a gene to reduce its production. Tofersen is an ASO against SOD1; others are being investigated against C9orf72.
Test what you've learned

Interactive quiz

Six questions to check what you take away. It grades itself: tap an answer and you'll instantly see whether you're right, with the explanation.

0 / 6Not answered yet